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Dissecting regulatory non-coding GWAS loci reveals fibroblast causal genes with pathophysiological relevance to heart failure

Author

Listed:
  • Richard Gill

    (Amgen Global Research
    Amgen R&D Postdoctoral Fellow Program
    University of California Davis)

  • Daniel R. Lu

    (Amgen Global Research)

  • Ittai Eres

    (Amgen Global Research)

  • Jiamiao Lu

    (Amgen Global Research)

  • Jixin Cui

    (Amgen Global Research)

  • Chen Wang

    (Amgen Global Research)

  • Zhongsheng J. Yu

    (Amgen Global Research)

  • Tracy Yamawaki

    (Amgen Global Research)

  • Hong Zhou

    (Amgen Global Research)

  • Baikang Pei

    (Amgen Global Research)

  • Junedh M. Amrute

    (Amgen Global Research
    Washington University School of Medicine)

  • Yen-Sin Ang

    (Amgen Global Research)

  • Songli Wang

    (Amgen Global Research)

  • Kory J. Lavine

    (Washington University School of Medicine)

  • Brandon Ason

    (Amgen Global Research)

  • Chi-Ming Li

    (Amgen R&D Postdoctoral Fellow Program
    Amgen Global Research
    Amgen Global Research)

  • Yi-Hsiang Hsu

    (Amgen Global Research
    Amgen R&D Postdoctoral Fellow Program
    Broad Institute of MIT and Harvard
    HSL Marcus Institute for Aging Research and Harvard Medical School)

Abstract

Heart failure is caused in part by cardiac remodeling processes that include the death of cardiac myocytes and their replacement by cardiac fibroblasts. Here, we hypothesize that cardiac fibroblasts may harbor epigenetic contexts in which heart disease-associated non-coding SNPs perturb gene expression relevant to disease. To test this, we utilized male primary cardiac fibroblasts to generate high-resolution Hi-C data and integrate it with functional genomic information to annotate and link putative distal regulatory elements in heart disease-associated loci to gene promoters. We identify several target genes with established roles in cardiac fibrosis and/or heart disease (GJA1, TBC1D32, CXCL12, IL6R, and FURIN). We perform Perturb-seq in immortalized male cardiac fibroblasts to knock out putative regulatory elements, confirming regulatory relationships involving GJA1, CXCL12, and FURIN. Our results demonstrate that multi-omic approaches can delineate pathophysiologically relevant regulatory circuits connecting protein-coding genes to non-coding genetic variants associated with disease.

Suggested Citation

  • Richard Gill & Daniel R. Lu & Ittai Eres & Jiamiao Lu & Jixin Cui & Chen Wang & Zhongsheng J. Yu & Tracy Yamawaki & Hong Zhou & Baikang Pei & Junedh M. Amrute & Yen-Sin Ang & Songli Wang & Kory J. Lav, 2025. "Dissecting regulatory non-coding GWAS loci reveals fibroblast causal genes with pathophysiological relevance to heart failure," Nature Communications, Nature, vol. 16(1), pages 1-17, December.
  • Handle: RePEc:nat:natcom:v:16:y:2025:i:1:d:10.1038_s41467-025-64070-1
    DOI: 10.1038/s41467-025-64070-1
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