Modeling delay in diagnosis of NF: under reportincg, incidence and prevalence estimates
AbstractIn this paper, we analyze data from the Italian National Register of Rare Diseases (NRRD) focusing, in particular, on the geo-temporal distribution of patients affected by neurofibromatosis type 1 (NF1, ICD9CM code 237.71). The aim is at deriving a corrected measure of incidence for the period 2007--2009 using a single source, and to provide NF1 prevalence estimates for the period 2001--2006 through the use of capture--recapture methods over two sources. In the first case, a reverse hazard estimator for the delay in diagnosis of NF1 is used to estimate the probability that a generic unit belonging to the population of interest has been registered by the archive of reference. For the second purpose, two-source capture--recapture methods have been used to estimate the number of NF1 prevalent units in Italy for the period 2001--2006, matching information provided by the NRRD and the national register of hospital discharge, Scheda di Dimissione Ospedaliera (in the following SDO), archives.
Download InfoIf you experience problems downloading a file, check if you have the proper application to view it first. In case of further problems read the IDEAS help page. Note that these files are not on the IDEAS site. Please be patient as the files may be large.
As the access to this document is restricted, you may want to look for a different version under "Related research" (further below) or search for a different version of it.
Bibliographic InfoArticle provided by Taylor & Francis Journals in its journal Journal of Applied Statistics.
Volume (Year): 39 (2012)
Issue (Month): 4 (August)
Contact details of provider:
Web page: http://www.tandfonline.com/CJAS20
You can help add them by filling out this form.
reading list or among the top items on IDEAS.Access and download statisticsgeneral information about how to correct material in RePEc.
For technical questions regarding this item, or to correct its authors, title, abstract, bibliographic or download information, contact: (Michael McNulty).
If you have authored this item and are not yet registered with RePEc, we encourage you to do it here. This allows to link your profile to this item. It also allows you to accept potential citations to this item that we are uncertain about.
If references are entirely missing, you can add them using this form.
If the full references list an item that is present in RePEc, but the system did not link to it, you can help with this form.
If you know of missing items citing this one, you can help us creating those links by adding the relevant references in the same way as above, for each refering item. If you are a registered author of this item, you may also want to check the "citations" tab in your profile, as there may be some citations waiting for confirmation.
Please note that corrections may take a couple of weeks to filter through the various RePEc services.